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5. Dynein mutations associated with hereditary motor neuropathies impair mitochondrial morphology and function with age. Eschbach J; Sinniger J; Bouitbir J; Fergani A; Schlagowski AI; Zoll J; Geny B; René F; Larmet Y; Marion V; Baloh RH; Harms MB; Shy ME; Messadeq N; Weydt P; Loeffler JP; Ludolph AC; Dupuis L Neurobiol Dis; 2013 Oct; 58():220-30. PubMed ID: 23742762 [TBL] [Abstract][Full Text] [Related]
6. Mutations in the tail domain of DYNC1H1 cause dominant spinal muscular atrophy. Harms MB; Ori-McKenney KM; Scoto M; Tuck EP; Bell S; Ma D; Masi S; Allred P; Al-Lozi M; Reilly MM; Miller LJ; Jani-Acsadi A; Pestronk A; Shy ME; Muntoni F; Vallee RB; Baloh RH Neurology; 2012 May; 78(22):1714-20. PubMed ID: 22459677 [TBL] [Abstract][Full Text] [Related]
7. Exome Sequencing Identifies De Novo DYNC1H1 Mutations Associated With Distal Spinal Muscular Atrophy and Malformations of Cortical Development. Chen Y; Xu Y; Li G; Li N; Yu T; Yao RE; Wang X; Shen Y; Wang J J Child Neurol; 2017 Mar; 32(4):379-386. PubMed ID: 28193117 [TBL] [Abstract][Full Text] [Related]
8. Novel mutations expand the clinical spectrum of DYNC1H1-associated spinal muscular atrophy. Scoto M; Rossor AM; Harms MB; Cirak S; Calissano M; Robb S; Manzur AY; Martínez Arroyo A; Rodriguez Sanz A; Mansour S; Fallon P; Hadjikoumi I; Klein A; Yang M; De Visser M; Overweg-Plandsoen WC; Baas F; Taylor JP; Benatar M; Connolly AM; Al-Lozi MT; Nixon J; de Goede CG; Foley AR; Mcwilliam C; Pitt M; Sewry C; Phadke R; Hafezparast M; Chong WK; Mercuri E; Baloh RH; Reilly MM; Muntoni F Neurology; 2015 Feb; 84(7):668-79. PubMed ID: 25609763 [TBL] [Abstract][Full Text] [Related]
9. DYNC1H1-related disorders: A description of four new unrelated patients and a comprehensive review of previously reported variants. Amabile S; Jeffries L; McGrath JM; Ji W; Spencer-Manzon M; Zhang H; Lakhani SA Am J Med Genet A; 2020 Sep; 182(9):2049-2057. PubMed ID: 32656949 [TBL] [Abstract][Full Text] [Related]
10. Mutation screen reveals novel variants and expands the phenotypes associated with DYNC1H1. Strickland AV; Schabhüttl M; Offenbacher H; Synofzik M; Hauser NS; Brunner-Krainz M; Gruber-Sedlmayr U; Moore SA; Windhager R; Bender B; Harms M; Klebe S; Young P; Kennerson M; Garcia AS; Gonzalez MA; Züchner S; Schule R; Shy ME; Auer-Grumbach M J Neurol; 2015 Sep; 262(9):2124-34. PubMed ID: 26100331 [TBL] [Abstract][Full Text] [Related]
11. Two cases of DYNC1H1 mutations with intractable epilepsy. Matsumoto A; Kojima K; Miya F; Miyauchi A; Watanabe K; Iwamoto S; Kawai K; Kato M; Takahashi Y; Yamagata T Brain Dev; 2021 Sep; 43(8):857-862. PubMed ID: 34092403 [TBL] [Abstract][Full Text] [Related]
12. Spinal muscular atrophy with predominant lower extremity (SMA-LED) with no signs other than pure motor symptoms at the intersection of multiple overlap syndrome. Tekin HG; Edem P; Özyılmaz B Brain Dev; 2022 Apr; 44(4):294-298. PubMed ID: 34974950 [TBL] [Abstract][Full Text] [Related]
13. Whole-exome sequencing identifies a novel de novo variant in DYNC1H in a patient with intractable epilepsy. Ji C; Wu D; Wang K Neurol Sci; 2022 Apr; 43(4):2853-2858. PubMed ID: 35088241 [TBL] [Abstract][Full Text] [Related]
14. DYNC1H1 mutation alters transport kinetics and ERK1/2-cFos signalling in a mouse model of distal spinal muscular atrophy. Garrett CA; Barri M; Kuta A; Soura V; Deng W; Fisher EM; Schiavo G; Hafezparast M Brain; 2014 Jul; 137(Pt 7):1883-93. PubMed ID: 24755273 [TBL] [Abstract][Full Text] [Related]
15. DYNC1H1 mutations associated with neurological diseases compromise processivity of dynein-dynactin-cargo adaptor complexes. Hoang HT; Schlager MA; Carter AP; Bullock SL Proc Natl Acad Sci U S A; 2017 Feb; 114(9):E1597-E1606. PubMed ID: 28196890 [TBL] [Abstract][Full Text] [Related]
16. Exome sequencing identifies a DYNC1H1 mutation in a large pedigree with dominant axonal Charcot-Marie-Tooth disease. Weedon MN; Hastings R; Caswell R; Xie W; Paszkiewicz K; Antoniadi T; Williams M; King C; Greenhalgh L; Newbury-Ecob R; Ellard S Am J Hum Genet; 2011 Aug; 89(2):308-12. PubMed ID: 21820100 [TBL] [Abstract][Full Text] [Related]
17. Mutations in DYNC1H1 cause severe intellectual disability with neuronal migration defects. Willemsen MH; Vissers LE; Willemsen MA; van Bon BW; Kroes T; de Ligt J; de Vries BB; Schoots J; Lugtenberg D; Hamel BC; van Bokhoven H; Brunner HG; Veltman JA; Kleefstra T J Med Genet; 2012 Mar; 49(3):179-83. PubMed ID: 22368300 [TBL] [Abstract][Full Text] [Related]
18. The clinical-phenotype continuum in DYNC1H1-related disorders-genomic profiling and proposal for a novel classification. Becker LL; Dafsari HS; Schallner J; Abdin D; Seifert M; Petit F; Smol T; Bok L; Rodan L; Krapels I; Spranger S; Weschke B; Johnson K; Straub V; Kaindl AM; Di Donato N; von der Hagen M; Cirak S J Hum Genet; 2020 Nov; 65(11):1003-1017. PubMed ID: 32788638 [TBL] [Abstract][Full Text] [Related]
19. A human dynein heavy chain mutation impacts cortical progenitor cells causing developmental defects, reduced brain size and altered brain architecture. Romero DM; Zaidi D; Cifuentes-Diaz C; Maillard C; Grannec G; Selloum M; Birling MC; Bahi-Buisson N; Francis F Neurobiol Dis; 2023 May; 180():106085. PubMed ID: 36933672 [TBL] [Abstract][Full Text] [Related]
20. DYNC1H1 de novo mutation, spinal muscular atrophy and attention problems. Fernández Perrone AL; Moreno Fernández P; Álvarez S; Fernández-Jaén A Neurologia (Engl Ed); 2022 Jun; 37(5):406-409. PubMed ID: 35606327 [No Abstract] [Full Text] [Related] [Next] [New Search]