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7. UBA5 Mutations Cause a New Form of Autosomal Recessive Cerebellar Ataxia. Duan R; Shi Y; Yu L; Zhang G; Li J; Lin Y; Guo J; Wang J; Shen L; Jiang H; Wang G; Tang B PLoS One; 2016; 11(2):e0149039. PubMed ID: 26872069 [TBL] [Abstract][Full Text] [Related]
8. Abnormal function of the UBA5 protein in a case of early developmental and epileptic encephalopathy with suppression-burst. Mignon-Ravix C; Milh M; Kaiser CS; Daniel J; Riccardi F; Cacciagli P; Nagara M; Busa T; Liebau E; Villard L Hum Mutat; 2018 Jul; 39(7):934-938. PubMed ID: 29663568 [TBL] [Abstract][Full Text] [Related]
9. A homozygous Cabrera-Serrano M; Coote DJ; Azmanov D; Goullee H; Andersen E; McLean C; Davis M; Ishimura R; Stark Z; Vallat JM; Komatsu M; Kornberg A; Ryan M; Laing NG; Ravenscroft G J Med Genet; 2020 Dec; 57(12):835-842. PubMed ID: 32179706 [TBL] [Abstract][Full Text] [Related]
10. Mechanistic study of Uba5 enzyme and the Ufm1 conjugation pathway. Gavin JM; Hoar K; Xu Q; Ma J; Lin Y; Chen J; Chen W; Bruzzese FJ; Harrison S; Mallender WD; Bump NJ; Sintchak MD; Bence NF; Li P; Dick LR; Gould AE; Chen JJ J Biol Chem; 2014 Aug; 289(33):22648-22658. PubMed ID: 24966333 [TBL] [Abstract][Full Text] [Related]
11. Biallelic UFM1 and UFC1 mutations expand the essential role of ufmylation in brain development. Nahorski MS; Maddirevula S; Ishimura R; Alsahli S; Brady AF; Begemann A; Mizushima T; Guzmán-Vega FJ; Obata M; Ichimura Y; Alsaif HS; Anazi S; Ibrahim N; Abdulwahab F; Hashem M; Monies D; Abouelhoda M; Meyer BF; Alfadhel M; Eyaid W; Zweier M; Steindl K; Rauch A; Arold ST; Woods CG; Komatsu M; Alkuraya FS Brain; 2018 Jul; 141(7):1934-1945. PubMed ID: 29868776 [TBL] [Abstract][Full Text] [Related]
12. Structural and Functional Analysis of a Novel Interaction Motif within UFM1-activating Enzyme 5 (UBA5) Required for Binding to Ubiquitin-like Proteins and Ufmylation. Habisov S; Huber J; Ichimura Y; Akutsu M; Rogova N; Loehr F; McEwan DG; Johansen T; Dikic I; Doetsch V; Komatsu M; Rogov VV; Kirkin V J Biol Chem; 2016 Apr; 291(17):9025-41. PubMed ID: 26929408 [TBL] [Abstract][Full Text] [Related]
13. Homozygous UBA5 Variant Leads to Hypomyelination with Thalamic Involvement and Axonal Neuropathy. Al-Saady ML; Kaiser CS; Wakasuqui F; Korenke GC; Waisfisz Q; Polstra A; Pouwels PJW; Bugiani M; van der Knaap MS; Lunsing RJ; Liebau E; Wolf NI Neuropediatrics; 2021 Dec; 52(6):489-494. PubMed ID: 33853163 [TBL] [Abstract][Full Text] [Related]
14. Biallelic loss-of-function UBA5 mutations in a patient with intractable West syndrome and profound failure to thrive. Daida A; Hamano SI; Ikemoto S; Matsuura R; Nakashima M; Matsumoto N; Kato M Epileptic Disord; 2018 Aug; 20(4):313-318. PubMed ID: 30078785 [TBL] [Abstract][Full Text] [Related]
15. De Novo Variants in CDK19 Are Associated with a Syndrome Involving Intellectual Disability and Epileptic Encephalopathy. Chung HL; Mao X; Wang H; Park YJ; Marcogliese PC; Rosenfeld JA; Burrage LC; Liu P; Murdock DR; Yamamoto S; Wangler MF; ; Chao HT; Long H; Feng L; Bacino CA; Bellen HJ; Xiao B Am J Hum Genet; 2020 May; 106(5):717-725. PubMed ID: 32330417 [TBL] [Abstract][Full Text] [Related]
16. Trans-binding of UFM1 to UBA5 stimulates UBA5 homodimerization and ATP binding. Mashahreh B; Hassouna F; Soudah N; Cohen-Kfir E; Strulovich R; Haitin Y; Wiener R FASEB J; 2018 May; 32(5):2794-2802. PubMed ID: 29295865 [TBL] [Abstract][Full Text] [Related]
17. Hemizygous UBA5 missense mutation unmasks recessive disorder in a patient with infantile-onset encephalopathy, acquired microcephaly, small cerebellum, movement disorder and severe neurodevelopmental delay. Low KJ; Baptista J; Babiker M; Caswell R; King C; Ellard S; Scurr I Eur J Med Genet; 2019 Feb; 62(2):97-102. PubMed ID: 29902590 [No Abstract] [Full Text] [Related]
18. Genetic model of UBA5 deficiency highlights the involvement of both peripheral and central nervous systems and identifies widespread mitochondrial abnormalities. Serrano RJ; Oorschot V; Palipana D; Calcinotto V; Sonntag C; Ramm G; Bryson-Richardson RJ Brain Commun; 2023; 5(6):fcad317. PubMed ID: 38046095 [TBL] [Abstract][Full Text] [Related]
19. A Concerted Action of UBA5 C-Terminal Unstructured Regions Is Important for Transfer of Activated UFM1 to UFC1. Wesch N; Löhr F; Rogova N; Dötsch V; Rogov VV Int J Mol Sci; 2021 Jul; 22(14):. PubMed ID: 34299007 [TBL] [Abstract][Full Text] [Related]
20. An N-Terminal Extension to UBA5 Adenylation Domain Boosts UFM1 Activation: Isoform-Specific Differences in Ubiquitin-like Protein Activation. Soudah N; Padala P; Hassouna F; Kumar M; Mashahreh B; Lebedev AA; Isupov MN; Cohen-Kfir E; Wiener R J Mol Biol; 2019 Feb; 431(3):463-478. PubMed ID: 30412706 [TBL] [Abstract][Full Text] [Related] [Next] [New Search]